Recurrent Hemoptysis in a Young Man

Madiha Mahfoudhi; Imen Gorsane; Mounira El Euch; Sami Turki; Taieb Ben Abdallah

doi:10.4236/ojim.2015.53006

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Open Journal of Internal Medicine > Vol.5 No.3, September 2015

Recurrent Hemoptysis in a Young Man ()

Madiha Mahfoudhi, Imen Gorsane, Mounira El Euch, Sami Turki, Taieb Ben Abdallah

Internal Medicine Department, Charles Nicolle Hospital, Tunis, Tunisia.

DOI: 10.4236/ojim.2015.53006 PDF HTML XML 3,690 Downloads 4,057 Views

Abstract

Hughes-Stovin syndrome is a scarce entity associating pulmonary artery aneurysms and deep venous thrombosis. It was considered to be a form of Behcet’s syndrome at its initial feature. We present a case of a 27-year-old man having a Hughes-Stovin syndrome. The patient had a history of left ilio-femoral thrombosis and suffered from recurrent oral ulcers. He presented with recurrent hemoptysis. A giant pulmonary aneurysm was confirmed by chest CT scan. A right femoral thrombosis was shown on the inferior legs doppler ultrasonography. The patient was treated by steroids and cyclophosphamide and proposed to an embolization to prevent recurrence of symptoms.

Keywords

Hemoptysis, Pulmonary Aneurysm, Hughes-Stovin Syndrome

Share and Cite:

Mahfoudhi, M. , Gorsane, I. , El Euch, M. , Turki, S. and Abdallah, T. (2015) Recurrent Hemoptysis in a Young Man. Open Journal of Internal Medicine, 5, 29-32. doi: 10.4236/ojim.2015.53006.

Conflicts of Interest

The authors declare no conflicts of interest.

References

[1]	Hughes, J.P. and Stovin, P.G.I. (1959) Segmental Pulmonary Artery Aneurysms with Peripheral Venous Thrombosis. British Journal of Diseases of the Chest, 53, 19-27. http://dx.doi.org/10.1016/S0007-0971(59)80106-6
[2]	Kindermann, M., Wilkens, H., Hartmann, W., Schäfers, H.J. and Böhm, M. (2003) Hughes-Stovin Syndrome. Circulation, 108, e156. http://dx.doi.org/10.1161/01.cir.0000106680.35316.16
[3]	Khalid, U. and Saleem, T. (2011) Hughes-Stovin Syndrome. Orphanet Journal of Rare Diseases, 6, 15. http://dx.doi.org/10.1186/1750-1172-6-15
[4]	Al-Jahdali, H. (2010) Massive Hemoptysis and Deep Venous Thrombosis Presenting in a Woman with Hughes-Stovin Syndrome: A Case Report. Journal of Medical Case Reports, 4, 109. http://dx.doi.org/10.1186/1752-1947-4-109
[5]	Chalazonitis, A.N., Lachanis, S.B., Mitseas, P., Argyriou, P., Tzovara, J., Porfyrides, P., et al. (2009) Hughes-Stovin Syndrome: A Case Report and Review of the Literature. Cases Journal, 2, 98. http://dx.doi.org/10.1186/1757-1626-2-98
[6]	Choh, N.A., Jehangir, M., Mir, K.M., Kuchay, S. and Wani, N.A. (2011) Hughes-Stovin Syndrome: A Rare Cause of Hemoptysis. Lung India, 28, 285-286. http://dx.doi.org/10.4103/0970-2113.85691
[7]	Ketchum, E., Zamanian, R. and Fleischmann, D. (2005) CT Angiography of Pulmonary Artery Aneurysms in Hughes- Stovin Syndrome. American Journal of Roentgenology, 185, 330-332. http://dx.doi.org/10.2214/ajr.185.2.01850330
[8]	Remy-Jardin, M, Bouaziz, N., Dumont, P., Brillet, P.Y., Bruzzi, J. and Remy J. (2004) Bronchial and Nonbronchial Systemic Arteries at Multi-Detector Row CT Angiography: Comparison with Conventional Angiography. Radiology, 233, 741-749. http://dx.doi.org/10.1148/radiol.2333040031
[9]	Lee, J., Noh, J.W., Hwang, J.W., Kim, H., Ahn, J.K., Koh, E.M., et al. (2005) Successful Cyclophosphamide Therapy with Complete Resolution of Pulmonary Artery Aneurysm in Hughes-Stovin Syndrome Patient. Clinical Rheumatology, 570, 570.
[10]	Tzilalis, V.D., Vourliotakis, G., Tsironis, I.A., Tsiligiris, V.D. and Brountzos, E.N. (2011) Use of an Amplatzer Vascular Plug in Embolization of a Pulmonary Artery Aneurysm in a Case of Hughes-Stovin Syndrome: A Case Report. Journal of Medical Case Reports, 5, 425. http://dx.doi.org/10.1186/1752-1947-5-425
[11]	Mangini, M., Laganà, D., Fontana, F., Ianniello, A., Nicotera, P., Petullà, M., et al. (2008) Use of Amplatzer Vascular Plug (AVP) in Emergency Embolisation: Preliminary Experience and Review of Literature. Emergency Radiology, 15, 153-160. http://dx.doi.org/10.1007/s10140-007-0696-8