Ileocolic Intussusception Prolapsing from the Rectum in von Recklinghausen's Disease

DOI: 10.4236/ss.2012.38084   PDF   HTML   XML   3,075 Downloads   4,686 Views  

Abstract

Intussusception is a paediatric condition that rarely presents in adults. We report an exceptional case of ileocolic intussusception prolapsing from the rectum in an adult with Von Recklinghausen′s disease. A 31-year-old man with von Recklinghausen′s disease presented to emergency department with a history of severe abdominal pain, vomits and rectal bleeding. Abdominal computed tomography showed intestinal obstruction probably due to a sigmoidorectal intussusception. Ileum, appendix, cecum and ascending colon were found to be intussuscepting through transverse, descending and sigmoid colon and prolapsing from the rectum during an emergent laparotomy. A right hemicolectomy was performed. An anatomical pathology examination revealed a neurofibroma of the appendix as lead point for intussusception. Intussusception in adults requires early surgical resection regardless of the nature of the initial case. Neurofibroma of the appendix is very rare; although it is benign, prompt resection is recommended because of a high risk of appendicitis and malignant transformation.

Share and Cite:

M. Canosa, L. Fernández, L. Castro, R. López, A. Gutiérrez, I. Ares, J. Vales and F. Val, "Ileocolic Intussusception Prolapsing from the Rectum in von Recklinghausen's Disease," Surgical Science, Vol. 3 No. 8, 2012, pp. 421-423. doi: 10.4236/ss.2012.38084.

Conflicts of Interest

The authors declare no conflicts of interest.

References

[1] N. Wang, X. Y. Cui, Y. Liu, J. Long, Y. Xu, R. Guo and K. Guo, “Adult Intussusception: A Retrospective Review of 41 Cases,” World Journal of Gastroenterology, Vol. 15, No. 26, 2009, pp. 3303-3308. doi:10.3748/wjg.15.3303
[2] B. Hanan, T. R. Diniz, M. M. P. Da Luz, S. A. Da Conceicao, R. G. Da Silva and A. Lacerda-Filho, “Intussusception in Adults: A Retrospective Study,” Colorectal Disease, Vol. 12, No. 6, 2010, pp. 574-578. doi:10.1111/j.1463-1318.2009.01865.x
[3] R. Chen, H. Zhao, X. Sang, Y. Mao, X. Lu and Y. Yang, “Severe Adult Ileosigmoid Intussusception Prolapsing from the Rectum: A Case Report,” Cases Journal, Vol. 1, 2008, p. 198. doi:10.1186/1757-1626-1-198
[4] U. Basile, G. Cavallaro, A. Polistena, S. Giustini, G. Orlando, D. Cotesta, L. Petramala, C. Letizia, S. Calvieri and G. De Toma, “Gastrointestinal and Retroperitoneal Manifestations of Type 1 Neurofibromatosis,” Journal of Gastrointestinal Surgery, Vol. 14, No. 1, 2010, pp. 186-194. doi:10.1007/s11605-009-0940-5
[5] S. Sugimoto, M. Takahashi, K. Nakagawa, T. Yabuno, F. Kito and S. Yoshida, “A Case of Neurofibroma of the Appendix in Von Recklinghausen Disease,” Nihon Shoka-kibyo Gakkai Zasshi, Vol. 108, No. 1, 2011, pp. 68-73.

  
comments powered by Disqus

Copyright © 2020 by authors and Scientific Research Publishing Inc.

Creative Commons License

This work and the related PDF file are licensed under a Creative Commons Attribution 4.0 International License.